Abstract
INTRODUCTION: Angioleiomyomas are benign smooth muscle tumors that arise from blood vessel walls and commonly involve the deep dermal and subcutaneous tissue. Urethral angioleiomyomas are only rarely seen with only less than 5 cases reported in literature. PRESENTATION OF CASE: We herein present a case of a 72 year old man who presented with gross hematuria. Cystoscopy showed a polypoid urethral lesion that was resected and on pathologic examination was diagnosed as angioleiomyoma. DISCUSSION: Differential diagnoses of a urethral polypoid lesion, including inflammatory and neoplastic conditions are discussed. The main emphasis is on recognition and review of angioleiomyoma features when presenting in commonly encountered locations and other sites that are only rarely involved. CONCLUSION: This rare case reports an elderly patient with angioleiomyoma in an extremely unusually encountered location and presenting with unusual symptoms of gross hematuria that did not recur after resection of the lesion.