Whipple's Disease, a Rare Cause of Constrictive Myopericarditis and Right-Sided Heart Failure

惠普尔病,一种罕见的缩窄性心肌心包炎和右心衰竭病因

阅读:2

Abstract

Whipple's disease is a rare, chronic multisystemic infection caused by Tropheryma whipplei. Although the disease typically presents with arthritis, diarrhea, fever, and lymphadenopathy, it may also involve the heart. Cardiac involvement is uncommon but may include constrictive myopericarditis, a potentially life-threatening cause of right-sided heart failure. We report the case of a 67-year-old woman admitted with decompensated right-sided heart failure. Echocardiography and chest CT revealed constrictive pericarditis with an intrapericardial mass initially suspicious for malignancy. Duodenal and pericardial biopsies demonstrated Periodic acid-Schiff (PAS)-positive macrophages, and polymerase chain reaction (PCR) confirmed T. whipplei infection. The patient had a history of chronic seronegative arthritis and later developed diarrhea and severe malnutrition, consistent with Whipple's disease. Standard antibiotic therapy was initiated with intravenous ceftriaxone, followed by trimethoprim-sulfamethoxazole. Her course was complicated by suspected immune reconstitution inflammatory syndrome, ongoing inflammation, and nutritional decline, rendering surgical pericardiectomy unsafe. A trial of oral corticosteroids in addition to antibiotics resulted in clinical improvement and significant regression of the pericardial mass. This case highlights an unusual cardiac manifestation of Whipple's disease and emphasizes the importance of considering this diagnosis in patients with unexplained constrictive pericarditis and systemic symptoms. To our knowledge, this is the first reported case of constrictive myopericarditis due to Whipple's disease successfully managed without pericardectomy. Our report underscores the potential role of a conservative medical approach in frail or high-risk patients and illustrates the need for a better understanding of immunopathogenesis to guide therapeutic strategies.

特别声明

1、本页面内容包含部分的内容是基于公开信息的合理引用;引用内容仅为补充信息,不代表本站立场。

2、若认为本页面引用内容涉及侵权,请及时与本站联系,我们将第一时间处理。

3、其他媒体/个人如需使用本页面原创内容,需注明“来源:[生知库]”并获得授权;使用引用内容的,需自行联系原作者获得许可。

4、投稿及合作请联系:info@biocloudy.com。