Abstract
PURPOSE: To report a case of bilateral contractile peripapillary staphyloma (CPS) examined by optical coherence tomography (OCT) and video recording. OBSERVATION: We report the clinical history of a male infant with bilateral CPS. Two ophthalmic examinations under general anesthesia were performed during follow-up examinations. During the first fundus examination when the infant was 4 months old, we observed staphylomatous excavation around the optic disc, an almost normal disc appearance at the bottom of the excavation, and irregular contraction bilaterally. OCT images showed deep excavation around the optic disc bilaterally and hyperreflective tissue beneath the sclera in the right eye. During the second examination when the child was 4 years and 1 month, in addition to the previous fundus findings, the fundus examination showed white fibrous tissue on the optic disc and pigmentation around the optic disc in the right eye and a retinal cyst in the left eye. Bilateral simultaneous video recordings showed that the contractions were not synchronized between the eyes. CONCLUSIONS: In a patient with bilateral CPS, we observed unsynchronized contraction between the eyes and the presence of sequential hyperreflective tissue under the sclera using bilateral ophthalmic approaches.