Multimodal Imaging Studies of Pigmented Paravenous Retinochoroidal Atrophy: A Case Report

色素性视网膜脉络膜旁静脉萎缩的多模态影像学研究:病例报告

阅读:2

Abstract

BACKGROUND Pigmented paravenous retinochoroidal atrophy (PPRCA) is a rare and poorly understood retinopathy, characterized by retinochoroidal atrophy and pigmentation along the retinal veins. Its etiology remains unclear; proposed mechanisms include inflammatory, developmental, and genetic factors. Here, we describe a 56-year-old woman who was diagnosed with PPRCA via multimodal imaging. CASE REPORT A 56-year-old Chinese woman presented with a 3-day history of vision deterioration in her left eye. Dilated fundus examination revealed bilateral pigment clumps and retinochoroidal atrophy along the retinal veins, which was more pronounced and displayed macular involvement in the left eye. Ultra-wide fundus fluorescein angiography showed hyperfluorescence consistent with retinal pigment epithelium degeneration, whereas fundus autofluorescence revealed hypoautofluorescent patches and hyperautofluorescence at lesion borders. Optical coherence tomography angiography demonstrated areas of flow void beneath the retinal pigment epithelium-Bruch membrane layer, suggestive of choriocapillaris hypoperfusion that corresponded with fundus autofluorescence findings. Spectral-domain optical coherence tomography showed absence of the myoid zone, ellipsoid zone, and interdigitation zone in the macular region, along with partial preservation of the retinal pigment epithelium. Based on these findings, a diagnosis of bilateral PPRCA was made. The patient was advised to undergo routine follow-up. CONCLUSIONS Multimodal imaging is essential to confirm the diagnosis of PPRCA. Optical coherence tomography angiography provides valuable insight into disease pathogenesis by demonstrating primary choriocapillaris involvement. Further research into genetic factors and potential therapeutic targets, including vascular endothelial growth factor inhibitors, is warranted to improve understanding and management of this condition.

特别声明

1、本页面内容包含部分的内容是基于公开信息的合理引用;引用内容仅为补充信息,不代表本站立场。

2、若认为本页面引用内容涉及侵权,请及时与本站联系,我们将第一时间处理。

3、其他媒体/个人如需使用本页面原创内容,需注明“来源:[生知库]”并获得授权;使用引用内容的,需自行联系原作者获得许可。

4、投稿及合作请联系:info@biocloudy.com。