Microvillus Inclusion Disease: Successful Treatment of Severe Hyponatremia With High-Dose Fludrocortisone via a Possible Gut-Mediated Mechanism

微绒毛包涵体病:高剂量氟氢可的松通过可能的肠道介导机制成功治疗严重低钠血症

阅读:1

Abstract

Microvillus inclusion disease (MVID) is a rare congenital enteropathy marked by severe secretory diarrhea and malabsorption due to microvillous atrophy secondary to accumulation of secretory granules in the apical cytoplasm of enterocytes. Management is supportive with parenteral nutrition and emergent management of acute electrolyte disturbances. We report an 8-month-old male infant with genetically confirmed MVID (MYO5B mutation) who developed life-threatening hyponatremia (serum sodium 118 mmol/L) despite maximal sodium supplementation (>300 mmol/d = 49 mmol/kg/d) and negligible urinary sodium level. High-dose fludrocortisone (100 mcg bid; 28.4 mcg/kg/d) successfully restored serum sodium levels and reduced stool output, with normalization of renin and aldosterone, without adverse effects. This case demonstrates a potential therapeutic benefit of gastrointestinal mineralocorticoid receptor agonism in managing severe hyponatremia in patients with MVID during periods of acute decompensation.

特别声明

1、本页面内容包含部分的内容是基于公开信息的合理引用;引用内容仅为补充信息,不代表本站立场。

2、若认为本页面引用内容涉及侵权,请及时与本站联系,我们将第一时间处理。

3、其他媒体/个人如需使用本页面原创内容,需注明“来源:[生知库]”并获得授权;使用引用内容的,需自行联系原作者获得许可。

4、投稿及合作请联系:info@biocloudy.com。