Solitary Plexiform Neurofibroma in the Urachus Associated With von Recklinghausen's Disease

脐尿管孤立性丛状神经纤维瘤与冯·雷克林豪森病相关

阅读:1

Abstract

Neurofibromatosis type 1 (NF1), also known as von Recklinghausen's disease, is an autosomal dominant disorder characterized by multiple café-au-lait macules and cutaneous neurofibromas. Although neurofibromas are common in NF1, involvement of the urinary tract is rare, with the bladder being the most frequently affected site. Urachal neurofibromas are extremely rare, and their diagnosis and management remain challenging due to nonspecific imaging characteristics and their often asymptomatic presentation. We report the case of a 30-year-old man with clinical features of NF1 in whom a 5-cm mass at the bladder dome was incidentally identified on MRI performed during evaluation for spinal cord symptoms. Imaging revealed a cone-shaped mass in the urachal region, and cystoscopy showed no mucosal abnormalities. Urinalysis and urine cytology were unremarkable. A transabdominal needle biopsy confirmed the diagnosis of a neurofibroma. Given the tumor's size (>5 cm) and deep-seated location in the trunk, both known risk factors for malignant transformation, surgical excision was performed, including resection of the urachus and bilateral umbilical ligaments. Histopathological analysis confirmed a plexiform neurofibroma consistent with NF1. The postoperative course was uneventful, with no evidence of recurrence during 36 months of follow-up. This case highlights the rare presentation of a urachal plexiform neurofibroma in a patient with NF1. To reduce the potential risk of malignant transformation associated with plexiform neurofibromas larger than 5 cm and located in deep trunk regions, accurate diagnosis and timely surgical intervention are essential, even in asymptomatic cases.

特别声明

1、本页面内容包含部分的内容是基于公开信息的合理引用;引用内容仅为补充信息,不代表本站立场。

2、若认为本页面引用内容涉及侵权,请及时与本站联系,我们将第一时间处理。

3、其他媒体/个人如需使用本页面原创内容,需注明“来源:[生知库]”并获得授权;使用引用内容的,需自行联系原作者获得许可。

4、投稿及合作请联系:info@biocloudy.com。