Refractory Antiphospholipid Syndrome With Thoracic Outlet and Superior Vena Cava Syndromes: A Complex Case of Recurrent Thrombosis

难治性抗磷脂综合征合并胸廓出口综合征和上腔静脉综合征:一例复杂的复发性血栓病例

阅读:1

Abstract

Thoracic outlet syndrome (TOS) and superior vena cava syndrome (SVCS) are rare and debilitating conditions that can cause vascular compression, hypercoagulable states, and central venous obstruction. This is the case of a 39-year-old female with treatment-resistant antiphospholipid syndrome (APS), hereditary angioedema (HAE), and mast cell activation syndrome (MCAS) complicated by SVCS and venous TOS. Her clinical course was further challenged by recurrent venous thromboembolism with treatment failure on multiple direct oral anticoagulants (DOACs), with warfarin being the only effective medication. Furthermore, the patient experienced several thrombotic events, which included: left subclavian vein thrombosis, recurrent deep vein thromboses (DVTs), and septic thrombophlebitis (methicillin-sensitive Staphylococcus epidermidis bacteremia) involving the left internal jugular vein. Her vascular history also included left lower lobectomy for pulmonary nodules and right cerebral stenting for reversible cerebral vasoconstriction syndrome (RCVS). The patient also had gastroparesis attributed to HAE-related visceral edema. This case illustrates the challenges posed by overlapping rare disorders, where the combination of APS and mechanical venous obstruction resulted in recurrent thromboses, complicated further by the patient's complex past medical history. Our findings highlight the limitations of conventional anticoagulation strategies in treatment-resistant APS and emphasize the need for multidisciplinary approaches.

特别声明

1、本页面内容包含部分的内容是基于公开信息的合理引用;引用内容仅为补充信息,不代表本站立场。

2、若认为本页面引用内容涉及侵权,请及时与本站联系,我们将第一时间处理。

3、其他媒体/个人如需使用本页面原创内容,需注明“来源:[生知库]”并获得授权;使用引用内容的,需自行联系原作者获得许可。

4、投稿及合作请联系:info@biocloudy.com。