Abstract
A cutaneous sinus tract of dental origin may easily be misdiagnosed and incorrectly treated. This paper reported a case of a 20-year-old male patient referred for a productive cutaneous sinus tract misdiagnosed by medical doctors for more than 4 years. The clinical and radiographic examinations confirmed the odontogenic origin related to a mandibular first right molar presenting an infected radicular cyst. Surgical treatment was performed leading to a significant healing of the sinus tract.